Combined cutaneous findings with segmental odontomaxillary dysplasia: Review of the literature and proposal of a new clinical classification
| Autor: | Farouk Bassam Rihani, Othman M. Yassin |
|---|---|
| Jazyk: | angličtina |
| Rok vydání: | 2008 |
| Předmět: |
medicine.medical_specialty
Radiographic imaging Case Report Lesion maxillofacial developmental anomaly Segmental odontomaxillary dysplasia Medicine Vermilion border hemimaxillofacial dysplasia Hypopigmentation Permanent teeth lcsh:R5-920 business.industry segmental odontomaxillary dysplasia Treatment options General Medicine medicine.disease Dermatology Surgery stomatognathic diseases medicine.anatomical_structure facial asymmetry medicine.symptom business lcsh:Medicine (General) Facial symmetry |
| Zdroj: | International Medical Case Reports Journal, Vol 2008, Iss default, Pp 7-11 (2008) International Medical Case Reports Journal |
| Popis: | Othman M Yassin1, Farouk B Rihani21Consultant in pediatric dentistry, Chairman of Pediatric Dentistry Specialty at King Hussien Medical Center, Royal Medical Services, Amman, Jordan; 2Specialist in pediatric dentistry, Prince Rashid Bin AL-Hassan Hospital, Royal Medical Services, Irbid, JordanAbstract: Segmental odontomaxillary dysplasia is characterized by variability of its clinical and radiological features, and may mimic other fibro-osseous lesions. We describe the case of a segmental odontomaxillary dysplasia in a 12-year-old male comprising of dermal, gingival, bony, and dental abnormalities. He presented with left midfacial diffuse hyperkeratotic erythematous lesion, ipsilateral hypopigmentation of upper lip with indistinct vermilion border, left-sided facial swelling, unilateral maxillary enlargement and ipsilateral failure of eruption of permanent teeth. Radiographic imaging showed abnormal bony trabeculation, impacted and missing teeth. Histopathologic findings showed characteristic features of segmental odontomaxillary dysplasia. We herein report a case of this rare unusual anomaly, review the literature, and propose a new clinical classification based on the limited number of previously reported cases in an attempt to categorize the clinical variants of the condition which might be helpful when treatment options are to be considered. Clinicians should be aware of its presence when encountering patients presenting with a facial cutaneous lesion especially when it is associated with facial asymmetry and unresponsive to treatment.Keywords: hemimaxillofacial dysplasia, segmental odontomaxillary dysplasia, facial asymmetry, maxillofacial developmental anomaly |
| Databáze: | OpenAIRE |
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