Late-onset isolated cystic hygroma: The obstetrical significance, management, and outcome

Autor: Gideon Shoshany, Shlomo Filmer, Bar Maor, Peter Jakobi, Ioseph Itskoviz, Israel Goldstein
Rok vydání: 1994
Předmět:
Zdroj: Prenatal Diagnosis. 14:757-761
ISSN: 1097-0223
0197-3851
DOI: 10.1002/pd.1970140818
Popis: We add two cases of prenatally diagnosed late-onset isolated cystic hygroma to the eight cases reported previously in the English literature. The obstetrical significance, management, and outcome of this entity are reviewed. A retrospective study of late-onset isolated cystic hygromas delivered in one medical centre between 1978 and 1992 was made. The medical records of these newborns served as the basis of the present report. A Medline search of the English literature was carried out. Over a period of 15 years, we observed 11 cases of late-onset congenital isolated cystic hygroma, two of whom had prenatal sonographic diagnosis. In one case, a Caesarean section was performed due to a huge lesion. All cases underwent surgical excision with a favourable outcome. Of the eight prenatally diagnosed cases reported previously, one died at birth due to inability to ventilate and two required a tracheostomy. Late-onset isolated cystic hygroma should be differentiated from the early-onset nuchal cystic hygroma. The differential diagnosis is important, as late-onset isolated cystic hygroma does not require any prenatal intervention, but special awareness during labour and Caesarean section in extreme cases. Transport to a perinatal centre with expert neonatal, respiratory, and paediatric surgical care is recommended. The prognosis in general is favourable.
Databáze: OpenAIRE