Vanishing Gastroschisis with a Favorable Outcome after a 3-Year Follow-Up: A Case Report and Literature Review.

Autor: Abi Rached E; Department of Gynaecology & Obstetrics, Hautepierre, University Hospital, Strasbourg, France., Sananes N; Department of Gynaecology & Obstetrics, Hautepierre, University Hospital, Strasbourg, France., Kauffmann-Chevalier I; Department of Pediatric Surgery, Hautepierre, University Hospital, Strasbourg, France., Becmeur F; Department of Pediatric Surgery, Hautepierre, University Hospital, Strasbourg, France.
Jazyk: angličtina
Zdroj: Case reports in obstetrics and gynecology [Case Rep Obstet Gynecol] 2020 Jan 07; Vol. 2020, pp. 8542087. Date of Electronic Publication: 2020 Jan 07 (Print Publication: 2020).
DOI: 10.1155/2020/8542087
Abstrakt: Vanishing gastroschisis (VG) is a severe complication of gastroschisis with a high mortality rate. We report here a case of VG with a favorable outcome after a 3-year follow-up. A 26-year-old primigravida woman was referred to Strasbourg University Hospital because her fetus was diagnosed with an isolated gastroschisis at 13-week gestation. The ultrasound evolution was marked by a progressive closure of the abdominal wall defect from 19-week gestation and the appearance of dilated intra-abdominal loops. The child was born with a closed abdominal wall except a small remnant at the level of the former gastroschisis orifice. Explorative laparotomy revealed extensive midgut atresia with only 50 cm of remaining midgut. A jejunocolic anastomosis was performed. The child is now 3 years old and has a favorable outcome with only 2 nights a week of parenteral nutrition. A total of 39 cases of VG type D from Perrone et al. classification are described in the literature from 1991 to 2019, among which 19 (48.7%) are alive at the time of publication but only 4 cases are described with a long-term follow-up of 3 years or more. This is the fifth case described with a favorable evolution after 3-year follow-up.
Competing Interests: The authors declare that they have no conflicts of interest.
(Copyright © 2020 Elise Abi Rached et al.)
Databáze: MEDLINE
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